Angiomyofibroblastoma of the retrorectal region: a case report

Angiomyofibroblastoma (AMFB) is a rare benign subcutaneous mesenchymal lesion. AMFB is mostly described in the vulvovaginal region with occasional cases reported in other female urogenital tract sites in women of reproductive age and early menopause, and in the male inguinoscrotal region. AMFB can clinically be misdiagnosed for Bartholin’s gland cyst or lipoma. A. 44-year-old female patient admitted firstly in December 2016 to gynecologic oncology department of Akdeniz University Medical Faculty. She had complaints of pelvic pain for the previous 8 months. A palpable, nontender solid mass lesion protruding to the left lateral wall of the vagina was observed. Bimanual examination detected a mobile mass measuring 8 x 7 cm in the retrorectal region, communicating with vagina. The patient was operated in January 2017 in collaboration with department of general surgery. Her postoperative period was uneventful, and she was discharged and future control visit was arrange. Surgical specimen appeared as an opalescent-white solid mass measuring 7 x 6 cm.Its microscopic examination revealed a well-circumscribed lesion containing spindle, and epitheloid cells. Based on histological findings, the diagnosis of angiomyofibroblastoma was made. Close postoperative follow-up was decided for the patient. Postoperative 7. month gynecologic controls of the patient did not reveal any pathologic finding. In summary, AMFB of the retrorectal region is extremely rare and is diagnostically challenging. Because of the benign behavior of AMFB with rare local recurrence, excluding other neoplasms and making the accurate diagnosis based on histological features is important.

Retrorektal bölge anjiomyofibroblastomu: Olgu Sunumu

Anjiomyofibroblastoma nadir benign subkutanöz mezenkimal lezyondur. Sýklýkla reproduktif yaþ ve erken menopozdaki kadýnlarda vulvovajinal bölgede tanýmlanýr, diðer kadýn ürogenital traktus alanlarýnda da tanýmlanmýþtýr; erkek inguinoskrotal bölgede de tanýmlanmaktadýr.Bartolin gland kisti ya da lipoma ile klinik olarak karýþabiliir. 44 yaþýnda bayan hasta Akdeniz Üniversitesi Týp Fakültesi Jinekolojik Onkoloji bölümüne Aralýk 2016 tarihinde baþvurdu. 8 aydýr devam eden pelvik aðrý þikayeti mevcuttu. Palpabl, sol lateral vajinal duvara protrude solid hassas olmayan lezyon gözlendi. Bimanuel muayenede retrorektal bölgede vajina ile iliþkili 8x7 cm mobil kitle gözlendi. Hasta Ocak 2017 tarihinde genel cerrahi bölümü ile birlikte opere edildi. Ameliyat sonrasý dönemde problem yaþamayan hasta kontrol ve takip önerilerek hastaneden taburcu edildi. Spesimenin patolojik incelemesinde opak beyaz 7x 6 cm solid kitle gözlendi, kitlenin mikroskopik incelemesinde iyi sýnýrlý spindle ve epiteloid hücre içeren lezyon gözlendi. Histolojik bulgulara dayanýlarak anjiomyofibroblastom tanýsý konuldu. Yakýn postoperatif takip planlanan hastanýn ameliyat sonrasý 7. ay kontrolünde anormal bulguya rastlanýlmadý.
Özet olarak, retrorektal bölge anjiomyofibroblastomu oldukça nadir ve tanýsý zor bir tümördür. AMFB'nin benign davranýþý, nadir lokal rekürrensi nedeniyle diðer neoplazileri dýþlamak ve histolojik özelliklere dayanarak doðru tanýyý koymak önemlidir.